先天性牙槽粘连伴腭裂1例

doi:10.13591/j.cnki.kqyx.2023.03.011

摘要/Abstract

摘要：

口腔粘连是指上颌骨和下颌骨之间的纤维或软组织粘连,这些粘连可以出现在口腔的不同位置,牙槽粘连为其表现之一。牙槽粘连是一种罕见的先天性畸形,很少独立存在,常伴有其他先天性缺陷,如唇裂、腭裂、微小舌、小颌畸形或颞下颌关节异常,其中腭裂最为常见。现报道1例先天性牙槽粘连伴腭裂患儿,经过手术治疗后创口愈合良好,并讨论其病因及治疗。

关键词: 先天性口腔粘连, 先天性牙槽粘连, 腭裂

Abstract:

An oral synechia is a fibrous or soft tissue adhesion between the maxilla and the mandible. These synechiae can appear at various locations in the oral cavity, with alveolar synechia being one of the manifestations. Alveolar synechia is a rare congenital deformity and often accompanied by additional congenital defects, such as cleft lip or palate, microglossia, micrognathia, or TMJ anomalies. Among these, cleft palate is the most common. A case of congenital alveolar synechiae with cleft palate is reported. The child is in good condition after surgical treatment. The etiology and treatment are discussed.

Key words: congenital oral synechia, congenital alveolar synechia, cleft palate

中图分类号:

R782.23

王子俊, 陈京京, 苏吉梅. 先天性牙槽粘连伴腭裂1例[J]. 口腔医学, 2023, 43(3): 248-251.

WANG Zijun, CHEN Jingjing, SU Jimei. Congenital alveolar synechiae with cleft palate: A case report[J]. Stomatology, 2023, 43(3): 248-251.

图/表 3

图1

图2

表1

参考文献 21

[1]	Dongol A, Acharya P, Prasad JN, et al. A veil in the oral cavity: Report of two cases of oral synechiae[J]. Int J Oral Maxillofac Surg, 2017, 46(3):286-288.
[2]	Ogino A, Onish K, Maruyama Y. Congenital oral synechia associated with cleft palate: Cleft palate medial synechia syndrome?[J]. Eur J Plast Surg, 2005, 27(7):338-340. doi: 10.1007/s00238-004-0685-z
[3]	Sybil D, Sagtani A. Cleft palate lateral synechiasyndrome[J]. Natl J Maxillofac Surg, 2013, 4(1):87-89. doi: 10.4103/0975-5950.117876
[4]	Imai Y, Tachi M. Congenital lateral palatal synechia associated with cleft palate: A case report with long-term follow-up and review of the literature[J]. Cleft Palate Craniofac J, 2020, 57(6):778-781. doi: 10.1177/1055665619896687
[5]	高岩. 口腔组织病理学[M]. 8版. 北京: 人民卫生出版社, 2020.
[6]	Garca MF, Goktas U, Isik Y, et al. Is the coexistence of intraoral synechiaand cleft palate anomaly a sequence?[J]. J Craniofac Surg, 2012, 23(3):e194-e195. doi: 10.1097/SCS.0b013e31824de3bf
[7]	Gupta RK, Jadhav V, Gupta A, et al. Congenital alveolar fusion[J]. J Pediatr Surg, 2008, 43(8):1421-1425. doi: 10.1016/j.jpedsurg.2007.12.072 pmid: 18675628
[8]	Naidoo S, Bütow KW. Nonsyndromic palate Synechia with floor of mouth[J]. Ann Maxillofac Surg, 2015, 5(1):100-103. doi: 10.4103/2231-0746.161102 pmid: 26389045
[9]	Zalan AK, Zubairy KK, Niazi M, et al. Congenital isolated bilateral soft tissue syngnathia in A 4-day old baby boy[J]. J Ayub Med Coll Abbottabad, 2021, 33(1):159-161.
[10]	李胜利, 罗国阳. 胎儿畸形产前超声诊断学[M]. 2版. 北京: 科学出版社, 2017:721-782.
[11]	Cerrati EW, Ahmed OH, Rickert SM. Isolated congenital maxillomandibular synechiae[J]. Am J Otolaryngol, 2015, 36(5):707-709. doi: 10.1016/j.amjoto.2015.04.008
[12]	Salahuddin O, Yousaf K, Rashid M, et al. Congenital alveolar synechiae with cleft palate[J]. J Pak Med Assoc, 2014, 64(6):703-704. pmid: 25252496
[13]	Sahin U, Ozdil K, Uscetin I, et al. Cleft palate and congenital alveolar synechiae syndrome[J]. Plast Reconstr Surg, 2005, 115(4):1212-1213. pmid: 15793474
[14]	Murphy SM, Rea S, McGovern E, et al. Cleft palate and congenital synechiae syndrome: A case report[J]. Cleft Palate Craniofac J, 2004, 41(2):206-207. doi: 10.1597/02-167
[15]	Dalal M, Davison PM. Cleft palate congenital alveolar synechiae syndrome: Case reports and review[J]. Br J Plast Surg, 2002, 55(3):256-257. pmid: 12041983
[16]	Cronin ED, Jabor M, Shayani P. Cleft palate lateral synechiasyndrome[J]. Plast Reconstr Surg, 2001, 108(5):1281-1283. pmid: 11604632
[17]	李翠平, 刘志良, 刘淑兰. 先天性上下牙槽粘连分离术一例报告[J]. 华西口腔医学杂志, 1996, 14(2):107.
[18]	Haramis HT, Apesos J. Cleft palate and congenital lateral alveolar synechia syndrome: Case presentation and literature review[J]. Ann Plast Surg, 1995, 34(4):424-430. doi: 10.1097/00000637-199504000-00016
[19]	Verdi GD, Neal BO. Cleft palate and congenital alveolar synechiaesyndrome[J]. Plast Reconstr Surg, 1984, 74(5):684-686. pmid: 6494324
[20]	Nakata NMK, Guion-Almeida ML, Costa R. Cleft palate-lateral synechiae syndrome: Report on three new patients with additional findings and evidence for variability and heterogeneity[J]. Am J Med Genet, 1993, 47(3):330-332. doi: 10.1002/(ISSN)1096-8628
[21]	Donepudi SK, Stocks RMS, Pivnick EK, et al. Cleft palate lateral synechia syndrome: An opportunity for unique surgical closure[J]. Int J Pediatr Otorhinolaryngol, 2009, 73(6):861-866. doi: 10.1016/j.ijporl.2009.03.008

作者及时间	就诊年龄	临床表现	口内检查	麻醉方式	手术器械	预后
本病例	3天	喂养困难	AS、CP	基础麻醉	电刀	发育正常
Zalan等(2021)^[9]	4天	喂养困难	AS	经鼻插管全身麻醉+ 利多卡因局部麻醉	手术刀	发育正常
Cerrati等(2015)^[11]	1天	喂养困难	AS	利多卡因局部麻醉	手术剪刀	发育正常
Salahuddin等 (2014)^[12]	15天	喂养困难	AS、CP	利多卡因局部麻醉	手术刀	发育正常
Sahin等(2005)^[13]	8个月	轻度颞下颌关节强直	AS、CP	气管插管全身麻醉	手术剪刀电刀	关节恢复、发育正常
Murphy等(2004)^[14]	1天	喂养困难	AS、CP	面罩给药全身麻醉	电刀	发育正常
Dalal等(2002)^[15]	2天(弟弟)	喂养困难	AS(前牙区薄组织带)、CP	无麻醉	剪刀	发育正常
	3个月(哥哥)	正常喂养	AS(后牙区厚组织带)、CP	—	—	自行断裂,发育正常
Cronin等(2001)^[16]	4个月	正常喂养	AS、CP	经口气管插管全身麻醉	手术刀	—
李翠平等(1996)^[17]	1天	喂养困难	AS	无麻醉	手术刀	发育正常
Haramis等 (1995)^[18]	2天	喂养困难	AS、CP	—	剪刀、电刀	发育正常
Verdi等(1984)^[19]	即刻	喂养困难	AS、CP	无麻醉	手术刀	发育正常